دورية أكاديمية
Communicating multiple tubular enteric duplication with toxic megacolon in an infant: A case report.
| العنوان: | Communicating multiple tubular enteric duplication with toxic megacolon in an infant: A case report. |
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| المؤلفون: | Jang E; Department of Surgery, Seoul St. Mary's Hospital, The Catholic University of Korea, Seoul, Korea., Chung JH |
| المصدر: | Medicine [Medicine (Baltimore)] 2021 May 07; Vol. 100 (18), pp. e25772. |
| نوع المنشور: | Case Reports; Journal Article |
| اللغة: | English |
| بيانات الدورية: | Publisher: Lippincott Williams & Wilkins Country of Publication: United States NLM ID: 2985248R Publication Model: Print Cited Medium: Internet ISSN: 1536-5964 (Electronic) Linking ISSN: 00257974 NLM ISO Abbreviation: Medicine (Baltimore) Subsets: MEDLINE |
| أسماء مطبوعة: | Original Publication: Hagerstown, Md : Lippincott Williams & Wilkins |
| مواضيع طبية MeSH: | Digestive System Abnormalities/*complications , Emergency Treatment/*methods , Intestinal Obstruction/*diagnosis , Intestines/*abnormalities , Megacolon, Toxic/*diagnosis, Colostomy ; Decompression, Surgical/methods ; Digestive System Abnormalities/diagnosis ; Digestive System Abnormalities/surgery ; Humans ; Infant ; Intestinal Obstruction/etiology ; Intestinal Obstruction/surgery ; Intestines/diagnostic imaging ; Intestines/surgery ; Laparotomy ; Male ; Megacolon, Toxic/etiology ; Megacolon, Toxic/surgery ; Treatment Outcome ; Ultrasonography |
| مستخلص: | Rationale: Gastrointestinal tract duplication is a rare congenial anomaly which can be found anywhere along the gastrointestinal tract. While many patients are incidentally diagnosed during operation, in some cases it can present with severe gastrointestinal symptoms. In this case report, the patient presented with signs of toxic megacolon leading to rapid aggravation of inflammatory shock. Patient Concerns: A 49-day old male infant presented with fever, poor feeding, and severe abdominal distension. Diagnosis: Abdominal ultrasonography was done. During the examination, a foley catheter was inserted through the anus to evaluate bowel patency and enable rectal decompression. The tip of the foley catheter was located in a separate narrower tubular lumen adjacent to the distended rectum. These findings suggested possibility of a tubular duplication cyst of the rectum as the culprit for the bowel obstruction. Interventions: The patient underwent emergency laparotomy. Findings showed multiple tubular intestinal duplications involving the ileum, appendix, cecum, descending colon, sigmoid colon and rectum. The true lumen of the rectosigmoid colon was completely collapsed while the adjacent tubular cyst remained severely distended and stool passage was not possible. Decompression of the sigmoid colon was done with loop colostomy with both the wall of the true bowel and enteric cyst forming the colostomy orifice. Outcomes: After 40 days of postoperative care, the patient was discharged with no immediate complications. Four months after the initial operation, colostomy take-down and transanal rectal common wall division was done. No complications were observed. Lessons: To our knowledge, this is the first case to be reported where a rare presentation of intestinal duplication resulted in an acute presentation toxic megacolon. Such emergency cases can be effectively treated with emergency surgical bowel decompression and elective common wall division. Competing Interests: The authors have no conflicts of interests to disclose. (Copyright © 2021 the Author(s). Published by Wolters Kluwer Health, Inc.) |
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| تواريخ الأحداث: | Date Created: 20210505 Date Completed: 20210512 Latest Revision: 20231111 |
| رمز التحديث: | 20240829 |
| مُعرف محوري في PubMed: | PMC8104209 |
| DOI: | 10.1097/MD.0000000000025772 |
| PMID: | 33950968 |
| قاعدة البيانات: | MEDLINE |
Full Text Finder | تدمد: | 1536-5964 |
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| DOI: | 10.1097/MD.0000000000025772 |