دورية أكاديمية
أعرض في EDS

An update on long-term outcomes of pediatric follicular mucinosis over a 20-year period: a retrospective cohort study.

التفاصيل البيبلوغرافية
العنوان: An update on long-term outcomes of pediatric follicular mucinosis over a 20-year period: a retrospective cohort study.
المؤلفون: Jin MF; Mayo Clinic, Alix School of Medicine, Rochester, MN, USA., Ali NS; Department of Dermatology, Mayo Clinic, Rochester, MN, USA., Davis DMR; Department of Dermatology, Mayo Clinic, Rochester, MN, USA.; Department of Pediatric and Adolescent Medicine, Mayo Clinic, Rochester, MN, USA., Johnson EF; Department of Dermatology, Mayo Clinic, Rochester, MN, USA.; Department of Laboratory Medicine and Pathology, Mayo Clinic, Rochester, MN, USA., Gibson LE; Department of Dermatology, Mayo Clinic, Rochester, MN, USA.; Department of Laboratory Medicine and Pathology, Mayo Clinic, Rochester, MN, USA.
المصدر: International journal of dermatology [Int J Dermatol] 2023 Aug; Vol. 62 (8), pp. 1056-1059. Date of Electronic Publication: 2023 Mar 15.
نوع المنشور: Journal Article
اللغة: English
بيانات الدورية: Publisher: Blackwell Science Country of Publication: England NLM ID: 0243704 Publication Model: Print-Electronic Cited Medium: Internet ISSN: 1365-4632 (Electronic) Linking ISSN: 00119059 NLM ISO Abbreviation: Int J Dermatol Subsets: MEDLINE
أسماء مطبوعة: Publication: Oxford : Blackwell Science
Original Publication: Philadelphia, Lippincott.
مواضيع طبية MeSH: Mucinosis, Follicular*/diagnosis , Skin Neoplasms*/pathology , Mycosis Fungoides*/diagnosis , Mycosis Fungoides*/therapy , Mycosis Fungoides*/pathology, Humans ; Child ; Retrospective Studies ; Skin/pathology ; Cell Transformation, Neoplastic/pathology
مستخلص: Background: Follicular mucinosis (FM) is a rare disease characterized by mucin accumulation in the follicular unit. FM's etiology is still widely debated since its first description in 1957. Follicular mucinosis is usually reported to be benign in children, although reports of malignant transformation, most commonly mycosis fungoides, exist. The present project aims to demonstrate that children with a diagnosis of follicular mucinosis have positive long-term outcomes and do not develop mycosis fungoides.
Materials and Methods: This is a retrospective cohort study where patients with a diagnosis of follicular mucinosis ages 22 years and below were identified. Data surrounding the patient's diagnosis of FM, differential diagnosis, treatments, and long-term outcomes were collected. Patients who were lost to follow-up were contacted by phone for an update on the status of their skin and overall health.
Results: Out of 14 patients with follow-up information, none developed subsequent mycosis fungoides or other hematologic malignancies.
Conclusion: Pediatric patients with follicular mucinosis will likely present with limited disease and not experience malignant transformation.
(© 2023 the International Society of Dermatology.)
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تواريخ الأحداث: Date Created: 20230315 Date Completed: 20230630 Latest Revision: 20230630
رمز التحديث: 20230630
DOI: 10.1111/ijd.16639
PMID: 36919978
قاعدة البيانات: MEDLINE
الوصف
تدمد:1365-4632
DOI:10.1111/ijd.16639