دورية أكاديمية

Case report: Myelitis and ganglionitis, an atypical presentation of Hansen's disease.

التفاصيل البيبلوغرافية
العنوان: Case report: Myelitis and ganglionitis, an atypical presentation of Hansen's disease.
المؤلفون: Spitz CN; Post-Graduate Program in Neurology, Federal University of the State of Rio de Janeiro, Rio de Janeiro, Brazil.; Laboratory of Leprosy, Oswaldo Cruz Institute, Oswaldo Cruz Foundation (FIOCRUZ), Rio de Janeiro, Rio de Janeiro, Brazil.; Pedro Ernesto University Hospital, Rio de Janeiro State University, Rio de Janeiro, Brazil., Pitta IJR; Laboratory of Leprosy, Oswaldo Cruz Institute, Oswaldo Cruz Foundation (FIOCRUZ), Rio de Janeiro, Rio de Janeiro, Brazil.; Department of Neurology, Fluminense Federal University, Niterói, Rio de Janeiro, Brazil., Andrade L; Post-Graduate Program in Neurology, Federal University of the State of Rio de Janeiro, Rio de Janeiro, Brazil.; Laboratory of Leprosy, Oswaldo Cruz Institute, Oswaldo Cruz Foundation (FIOCRUZ), Rio de Janeiro, Rio de Janeiro, Brazil.; Pedro Ernesto University Hospital, Rio de Janeiro State University, Rio de Janeiro, Brazil., de Carvalho LB; Post-Graduate Program in Neurology, Federal University of the State of Rio de Janeiro, Rio de Janeiro, Brazil.; Laboratory of Leprosy, Oswaldo Cruz Institute, Oswaldo Cruz Foundation (FIOCRUZ), Rio de Janeiro, Rio de Janeiro, Brazil.; Pedro Ernesto University Hospital, Rio de Janeiro State University, Rio de Janeiro, Brazil., de Carvalho DMT; Pedro Ernesto University Hospital, Rio de Janeiro State University, Rio de Janeiro, Brazil., Schmidt FDR; Pedro Ernesto University Hospital, Rio de Janeiro State University, Rio de Janeiro, Brazil., Siquara de Sousa AC; Laboratory of Leprosy, Oswaldo Cruz Institute, Oswaldo Cruz Foundation (FIOCRUZ), Rio de Janeiro, Rio de Janeiro, Brazil., Mendonça SM; Clinical Diagnostic Imaging (CDPI), Rio de Janeiro, Rio de Janeiro, Brazil., Sarno EN; Laboratory of Leprosy, Oswaldo Cruz Institute, Oswaldo Cruz Foundation (FIOCRUZ), Rio de Janeiro, Rio de Janeiro, Brazil., Sales AM; Laboratory of Leprosy, Oswaldo Cruz Institute, Oswaldo Cruz Foundation (FIOCRUZ), Rio de Janeiro, Rio de Janeiro, Brazil., Pinheiro RO; Laboratory of Leprosy, Oswaldo Cruz Institute, Oswaldo Cruz Foundation (FIOCRUZ), Rio de Janeiro, Rio de Janeiro, Brazil.; National Institute of Science and Technology on Neuroimmunomodulation, Rio de Janeiro, Rio de Janeiro, Brazil., Jardim MR; Post-Graduate Program in Neurology, Federal University of the State of Rio de Janeiro, Rio de Janeiro, Brazil.; Laboratory of Leprosy, Oswaldo Cruz Institute, Oswaldo Cruz Foundation (FIOCRUZ), Rio de Janeiro, Rio de Janeiro, Brazil.; Pedro Ernesto University Hospital, Rio de Janeiro State University, Rio de Janeiro, Brazil.
المصدر: Frontiers in medicine [Front Med (Lausanne)] 2024 May 20; Vol. 11, pp. 1400423. Date of Electronic Publication: 2024 May 20 (Print Publication: 2024).
نوع المنشور: Case Reports; Journal Article
اللغة: English
بيانات الدورية: Publisher: Frontiers Media S.A Country of Publication: Switzerland NLM ID: 101648047 Publication Model: eCollection Cited Medium: Print ISSN: 2296-858X (Print) Linking ISSN: 2296858X NLM ISO Abbreviation: Front Med (Lausanne) Subsets: PubMed not MEDLINE
أسماء مطبوعة: Original Publication: Lausanne, Switzerland : Frontiers Media S.A., [2014]-
مستخلص: Hansen's disease, or leprosy, is a disease characterized by dermatological and neurological disorders. A neural form also exists, in which peripheral neuropathy occurs in the absence of skin lesions. However, cases of leprosy that involve the central nervous system and proximal nerves are rare in the literature. We describe the case of an oligosymptomatic patient diagnosed with the neural form of leprosy with involvement of peripheral nerves, dorsal root ganglion, and cervical spinal cord in an atypical presentation of the disease. Through complementary examinations and nerve biopsies, the bacillus was identified, and treatment was subsequently initiated. This case highlights the importance of investigating the suspicion of leprosy, even in cases with atypical manifestations, as early diagnosis and treatment can reduce neurological damage and deformities.
Competing Interests: The authors declare that the research was conducted in the absence of any commercial or financial relationships that could be construed as a potential conflict of interest.
(Copyright © 2024 Spitz, Pitta, Andrade, de Carvalho, de Carvalho, Schmidt, Siquara de Sousa, Mendonça, Sarno, Sales, Pinheiro and Jardim.)
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فهرسة مساهمة: Keywords: Hansen’s disease; atypical; central nervous system; resonance magnetic images; ulnar nerve; ultrasound imaging
تواريخ الأحداث: Date Created: 20240605 Latest Revision: 20240607
رمز التحديث: 20240607
مُعرف محوري في PubMed: PMC11149418
DOI: 10.3389/fmed.2024.1400423
PMID: 38835799
قاعدة البيانات: MEDLINE
الوصف
تدمد:2296-858X
DOI:10.3389/fmed.2024.1400423