دورية أكاديمية

Pulmonary mucoepidermoid carcinoma arising in a patient with Kartagener syndrome.

التفاصيل البيبلوغرافية
العنوان: Pulmonary mucoepidermoid carcinoma arising in a patient with Kartagener syndrome.
المؤلفون: Nagai, Yoshiaki, Koyama, Nobuyuki, Iwai, Yuki, Tsubochi, Hiroyoshi, Hiruta, Masahiro, Mizushina, Yoshiko, Koyama, Shinichiro, Ishikawa, Yuichi, Hagiwara, Koichi
المصدر: BMC Pulmonary Medicine; 4/16/2020, Vol. 20 Issue 1, p1-5, 5p, 2 Color Photographs, 2 Black and White Photographs
مصطلحات موضوعية: BRONCHIECTASIS, SITUS inversus, RESPIRATORY infections, SYNDROMES, CARCINOMA, SURGICAL site, TUMOR surgery, BRONCHOSCOPY, CHEST X rays, COMPUTED tomography, LUNG tumors, TUMORS, RESPIRATORY organ abnormalities, DISEASE complications
مصطلحات جغرافية: JAPAN
مستخلص: Background: Kartagener syndrome, an autosomal recessive disorder with a triad of chronic sinusitis, bronchiectasis, and situs inversus, is characterized by recurrent respiratory tract infections and chronic inflammation of the lung. Information on comorbidities other than infections in patients with Kartagener syndrome is currently limited.Case Presentation: A 39-year-old, non-smoking female was diagnosed with Kartagener syndrome and admitted to Saitama Medical Center, Jichi Medical University, Japan. Computed tomography revealed an endobronchial massive shadow at the ostial site of the right upper lobe bronchus with atelectasis of the right upper lobe. The mass was surgically resected and pathologically diagnosed as mucoepidermoid carcinoma. The lesion had no vascular invasions and no metastases to the lungs or lymph nodes. The surgical margin was negative for carcinoma. Following surgery, the patient has been in good condition.Conclusions: The present case showed different clinicopathological characteristics from those previously reported in cases of Kartagener syndrome complicated by carcinoma. To the best of our knowledge, this is the first reported case of a young, non-smoking female with comorbid Kartagener syndrome and pulmonary mucoepidermoid carcinoma. This case report may provide a new perspective on the complications of Kartagener syndrome. [ABSTRACT FROM AUTHOR]
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قاعدة البيانات: Complementary Index
الوصف
تدمد:14712466
DOI:10.1186/s12890-020-1133-y